Cost-effectiveness analysis of reflex testing for Lynch syndrome in women with endometrial cancer in the UK setting

cost-effectiveness analysis
diagnostic testing
endometrial cancer
genetic testing
Lynch syndrome
Markov model
Authors

Snowsill, T. M.

Ryan, N. A. J.

Crosbie, E. J.

Frayling, I. M.

Evans, D. G.

Hyde, C. J.

Published

Aug 2019

Abstract

BACKGROUND: Lynch syndrome is a hereditary cancer syndrome caused by constitutional pathogenic variants in the DNA mismatch repair (MMR) system, leading to increased risk of colorectal, endometrial and other cancers. The study aimed to identify the incremental costs and consequences of strategies to identify Lynch syndrome in women with endometrial cancer. METHODS: A decision-analytic model was developed to evaluate the relative cost-effectiveness of reflex testing strategies for identifying Lynch syndrome in women with endometrial cancer taking the NHS perspective and a lifetime horizon. Model input parameters were sourced from various published sources. Consequences were measured using quality-adjusted life years (QALYs). A cost-effectiveness threshold of pound20 000/QALY was used. RESULTS: Reflex testing for Lynch syndrome using MMR immunohistochemistry and MLH1 methylation testing was cost-effective versus no testing, costing pound14 200 per QALY gained. There was uncertainty due to parameter imprecision, with an estimated 42% chance this strategy is not cost-effective compared with no testing. Age had a significant impact on cost-effectiveness, with testing not predicted to be cost-effective in patients aged 65 years and over. CONCLUSIONS: Testing for Lynch syndrome in younger women with endometrial cancer using MMR immunohistochemistry and MLH1 methylation testing may be cost-effective. Age cut-offs may be controversial and adversely affect implementation.

Citation

BibTeX citation:
@article{t.m.2019,
  author = {Snowsill, T. M. and Ryan, N. A. J. and Crosbie, E. J. and
    Frayling, I. M. and Evans, D. G. and Hyde, C. J.},
  title = {Cost-Effectiveness Analysis of Reflex Testing for {Lynch}
    Syndrome in Women with Endometrial Cancer in the {UK} Setting},
  journal = {PLoS One},
  volume = {14},
  number = {8},
  pages = {e0221419},
  date = {2019-08-01},
  url = {https://tristansnowsill.co.uk/cost-effectiveness-analysis-of-reflex-testing-for-lynch.html},
  doi = {10.1371/journal.pone.0221419},
  langid = {en},
  abstract = {BACKGROUND: Lynch syndrome is a hereditary cancer syndrome
    caused by constitutional pathogenic variants in the DNA mismatch
    repair (MMR) system, leading to increased risk of colorectal,
    endometrial and other cancers. The study aimed to identify the
    incremental costs and consequences of strategies to identify Lynch
    syndrome in women with endometrial cancer. METHODS: A
    decision-analytic model was developed to evaluate the relative
    cost-effectiveness of reflex testing strategies for identifying
    Lynch syndrome in women with endometrial cancer taking the NHS
    perspective and a lifetime horizon. Model input parameters were
    sourced from various published sources. Consequences were measured
    using quality-adjusted life years (QALYs). A cost-effectiveness
    threshold of pound20 000/QALY was used. RESULTS: Reflex testing for
    Lynch syndrome using MMR immunohistochemistry and MLH1 methylation
    testing was cost-effective versus no testing, costing pound14 200
    per QALY gained. There was uncertainty due to parameter imprecision,
    with an estimated 42\% chance this strategy is not cost-effective
    compared with no testing. Age had a significant impact on
    cost-effectiveness, with testing not predicted to be cost-effective
    in patients aged 65 years and over. CONCLUSIONS: Testing for Lynch
    syndrome in younger women with endometrial cancer using MMR
    immunohistochemistry and MLH1 methylation testing may be
    cost-effective. Age cut-offs may be controversial and adversely
    affect implementation.}
}
For attribution, please cite this work as:
Snowsill, T. M., Ryan, N. A. J., Crosbie, E. J., Frayling, I. M., Evans, D. G., and Hyde, C. J. 2019. “Cost-Effectiveness Analysis of Reflex Testing for Lynch Syndrome in Women with Endometrial Cancer in the UK Setting.” PLoS One 14 (8): e0221419. https://doi.org/10.1371/journal.pone.0221419.