The predicted impact and cost-effectiveness of systematic testing of people with incident colorectal cancer for Lynch syndrome

colorectal cancer
cost-effectiveness analysis
diagnostic testing
genetic testing
Lynch syndrome
Markov model
Authors

Kang, Y. J.

Killen, J.

Caruana, M.

Simms, K.

Taylor, N.

Frayling, I. M.

Snowsill, T.

Huxley, N.

Coupe, V. M. H.

Hughes, S.

Freeman, V.

Boussioutas, A.

Trainer, A. H.

Ward, R. L.

Mitchell, G.

Macrae, F. A.

Canfell, K.

Published

Feb 2020

Abstract

Objectives: To evaluate the health impact and cost-effectiveness of systematic testing for Lynch syndrome (LS) in people with incident colorectal cancer (CRC) in Australia. Design, setting, participants: We investigated the impact of LS testing strategies in a micro-simulation model (Policy1–Lynch), explicitly modelling the cost of testing all patients diagnosed with incident CRC during 2017, with detailed modelling of outcomes for patients identified as LS carriers (probands) and their at-risk relatives throughout their lifetimes. For people with confirmed LS, we modelled ongoing colonoscopic surveillance. Main outcome measures: Cost-effectiveness of six universal tumour testing strategies (testing for DNA mismatch repair deficiencies) and of universal germline gene panel testing of patients with incident CRC; impact on cost-effectiveness of restricting testing by age at CRC diagnosis (all ages, under 50/60/70 years) and of colonoscopic surveillance interval (one, two years). Results: The cost-effectiveness ratio of universal tumour testing strategies (annual colonoscopic surveillance, no testing age limit) compared with no testing ranged from $28,915 to $31,904/life-year saved (LYS) (indicative willingness-to-pay threshold: $30,000–$50,000/LYS). These strategies could avert 184–189 CRC deaths with an additional 30,597–31,084 colonoscopies over the lifetimes of 1000 patients with incident CRC with LS and 1420 confirmed LS carrier relatives (164–166 additional colonoscopies/death averted). The most cost-effective strategy was immunohistochemistry and BRAF V600E testing (incremental cost-effectiveness ratio [ICER], $28,915/LYS). Universal germline gene panel testing was not cost-effective compared with universal tumour testing strategies (ICER, $2.4million/LYS). Immunohistochemistry and BRAF V600E testing was cost-effective at all age limits when paired with 2-yearly colonoscopic surveillance (ICER, $11,525–$32,153/LYS), and required 4778–15,860 additional colonoscopies to avert 46–181 CRC deaths (88–103 additional colonoscopies/death averted). Conclusions: Universal tumour testing strategies for guiding germline genetic testing of people with incident CRC for LS in Australia are likely to be cost-effective compared with no testing. Universal germline gene panel testing would not currently be cost-effective.

Citation

BibTeX citation:
@article{y.j.2020,
  author = {Kang, Y. J. and Killen, J. and Caruana, M. and Simms, K. and
    Taylor, N. and Frayling, I. M. and Snowsill, T. and Huxley, N. and
    Coupe, V. M. H. and Hughes, S. and Freeman, V. and Boussioutas, A.
    and Trainer, A. H. and Ward, R. L. and Mitchell, G. and Macrae, F.
    A. and Canfell, K.},
  title = {The Predicted Impact and Cost-Effectiveness of Systematic
    Testing of People with Incident Colorectal Cancer for {Lynch}
    Syndrome},
  journal = {Medical Journal of Australia},
  volume = {212},
  number = {2},
  pages = {72-81},
  date = {2020-02-01},
  url = {https://tristansnowsill.co.uk/the-predicted-impact-and-cost-effectiveness-of.html},
  doi = {10.5694/mja2.50356},
  langid = {en},
  abstract = {Objectives: To evaluate the health impact and
    cost-effectiveness of systematic testing for Lynch syndrome (LS) in
    people with incident colorectal cancer (CRC) in Australia. Design,
    setting, participants: We investigated the impact of LS testing
    strategies in a micro-simulation model (Policy1–Lynch), explicitly
    modelling the cost of testing all patients diagnosed with incident
    CRC during 2017, with detailed modelling of outcomes for patients
    identified as LS carriers (probands) and their at-risk relatives
    throughout their lifetimes. For people with confirmed LS, we
    modelled ongoing colonoscopic surveillance. Main outcome measures:
    Cost-effectiveness of six universal tumour testing strategies
    (testing for DNA mismatch repair deficiencies) and of universal
    germline gene panel testing of patients with incident CRC; impact on
    cost-effectiveness of restricting testing by age at CRC diagnosis
    (all ages, under 50/60/70 years) and of colonoscopic surveillance
    interval (one, two years). Results: The cost-effectiveness ratio of
    universal tumour testing strategies (annual colonoscopic
    surveillance, no testing age limit) compared with no testing ranged
    from \$28,915 to \$31,904/life-year saved (LYS) (indicative
    willingness-to-pay threshold: \$30,000–\$50,000/LYS). These
    strategies could avert 184–189 CRC deaths with an additional
    30,597–31,084 colonoscopies over the lifetimes of 1000 patients with
    incident CRC with LS and 1420 confirmed LS carrier relatives
    (164–166 additional colonoscopies/death averted). The most
    cost-effective strategy was immunohistochemistry and BRAF V600E
    testing (incremental cost-effectiveness ratio {[}ICER{]},
    \$28,915/LYS). Universal germline gene panel testing was not
    cost-effective compared with universal tumour testing strategies
    (ICER, \$2.4million/LYS). Immunohistochemistry and BRAF V600E
    testing was cost-effective at all age limits when paired with
    2-yearly colonoscopic surveillance (ICER, \$11,525–\$32,153/LYS),
    and required 4778–15,860 additional colonoscopies to avert 46–181
    CRC deaths (88–103 additional colonoscopies/death averted).
    Conclusions: Universal tumour testing strategies for guiding
    germline genetic testing of people with incident CRC for LS in
    Australia are likely to be cost-effective compared with no testing.
    Universal germline gene panel testing would not currently be
    cost-effective.}
}
For attribution, please cite this work as:
Kang, Y. J., Killen, J., Caruana, M., Simms, K., Taylor, N., Frayling, I. M., Snowsill, T., et al. 2020. “The Predicted Impact and Cost-Effectiveness of Systematic Testing of People with Incident Colorectal Cancer for Lynch Syndrome.” Medical Journal of Australia 212 (2): 72–81. https://doi.org/10.5694/mja2.50356.